Lichen sclerosus in children often leads to serious complications due to lack of early understanding and management of the disease.This paper reports a case of Lichen sclerosus in children with severe malformation of the urethral meatus of the penis.The patient was treated at a local hospital for preputial stenosis and dysuria,and cicatricial phimosis was considered.During the operation,due to the rigid inner plate of the foreskin,the penile head of the foreskin was severely adherent and could not be separated,and the circumcising operation failed.Only the narrow ring of the foreskin on the back of the penis was cut to solve the difficulty of urination,resulting in serious malformations of the meatus of the penile head.Subsequently,the patient was treated in our hospital for cicatricial adhesion release,circumcision and external urethral ostium plastic surgery.The postoperative pathology showed sclerosing lichenoid degeneration.After 1 year follow-up,the appearance was satisfactory and urination was smooth.